Adult-onset woakes' syndrome: Report of two cases
Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two ne...
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Veröffentlicht in: | Annals of medicine and surgery 2021-09, Vol.69, p.102695, Article 102695 |
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description | Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases.
We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed.
having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed.
These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery.
•Woakes' syndrome is an extremely rare clinical condition.•Self-medication and chronic evolution seemed to be factors to develop woakes' syndrome.•External nose deformity may be successfully corrected by forced external digital compression without osteotomies. |
doi_str_mv | 10.1016/j.amsu.2021.102695 |
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We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed.
having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed.
These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery.
•Woakes' syndrome is an extremely rare clinical condition.•Self-medication and chronic evolution seemed to be factors to develop woakes' syndrome.•External nose deformity may be successfully corrected by forced external digital compression without osteotomies.</description><identifier>ISSN: 2049-0801</identifier><identifier>EISSN: 2049-0801</identifier><identifier>DOI: 10.1016/j.amsu.2021.102695</identifier><identifier>PMID: 34457252</identifier><language>eng</language><publisher>England: Elsevier Ltd</publisher><subject>Adult male ; Case Report ; Digital compression ; Nasal dorsum deformity ; Nasal polyps ; Sinonasal surgery ; Woakes' syndrome</subject><ispartof>Annals of medicine and surgery, 2021-09, Vol.69, p.102695, Article 102695</ispartof><rights>2021 The Authors</rights><rights>2021 The Authors.</rights><rights>2021 The Authors 2021</rights><lds50>peer_reviewed</lds50><oa>free_for_read</oa><woscitedreferencessubscribed>false</woscitedreferencessubscribed><orcidid>0000-0002-2862-8102 ; 0000-0002-2325-4930</orcidid></display><links><openurl>$$Topenurl_article</openurl><openurlfulltext>$$Topenurlfull_article</openurlfulltext><thumbnail>$$Tsyndetics_thumb_exl</thumbnail><linktopdf>$$Uhttps://www.ncbi.nlm.nih.gov/pmc/articles/PMC8377525/pdf/$$EPDF$$P50$$Gpubmedcentral$$Hfree_for_read</linktopdf><linktohtml>$$Uhttps://www.ncbi.nlm.nih.gov/pmc/articles/PMC8377525/$$EHTML$$P50$$Gpubmedcentral$$Hfree_for_read</linktohtml><link.rule.ids>230,314,723,776,780,881,27901,27902,53766,53768</link.rule.ids><backlink>$$Uhttps://www.ncbi.nlm.nih.gov/pubmed/34457252$$D View this record in MEDLINE/PubMed$$Hfree_for_read</backlink></links><search><creatorcontrib>Chennoufi, Ilham</creatorcontrib><creatorcontrib>Bendiouri, Reda</creatorcontrib><creatorcontrib>Lachkar, Azeddine</creatorcontrib><creatorcontrib>Drissia, Belfadil</creatorcontrib><creatorcontrib>Abdenbi Tsen, Adil</creatorcontrib><creatorcontrib>Elayoubi, Fahd</creatorcontrib><creatorcontrib>Ghailan, Rachid</creatorcontrib><title>Adult-onset woakes' syndrome: Report of two cases</title><title>Annals of medicine and surgery</title><addtitle>Ann Med Surg (Lond)</addtitle><description>Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases.
We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed.
having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed.
These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery.
•Woakes' syndrome is an extremely rare clinical condition.•Self-medication and chronic evolution seemed to be factors to develop woakes' syndrome.•External nose deformity may be successfully corrected by forced external digital compression without osteotomies.</description><subject>Adult male</subject><subject>Case Report</subject><subject>Digital compression</subject><subject>Nasal dorsum deformity</subject><subject>Nasal polyps</subject><subject>Sinonasal surgery</subject><subject>Woakes' syndrome</subject><issn>2049-0801</issn><issn>2049-0801</issn><fulltext>true</fulltext><rsrctype>article</rsrctype><creationdate>2021</creationdate><recordtype>article</recordtype><recordid>eNp9kE1Lw0AQhhdRrNT-AQ-Sm6fU_chmExGhFL-gIIiel_2Y6NYmW3bTlv57U6KlXjwMM8zM-w7zIHRB8Jhgkl_Px6qOqzHFlHQNmpf8CJ1RnJUpLjA5PqgHaBTjHGNMMGd5XpyiAcsyLiinZ4hM7GrRpr6J0CYbr74gXiVx29jga7hJXmHpQ5v4Kmk3PjEqQjxHJ5VaRBj95CF6f7h_mz6ls5fH5-lklhomWJsyQqzWnBOt8txQQ3WFdReVtsIaoRWtDCeCcKiE0ra0jJaW44yRgipcFGyI7nrf5UrXYA00bVALuQyuVmErvXLy76Rxn_LDr2XBhOCUdwa0NzDBxxig2msJljuGci53DOWOoewZdqLLw6t7yS-xbuG2X4Du97WDIKNx0BiwLoBppfXuP_9vdJ2DkQ</recordid><startdate>20210901</startdate><enddate>20210901</enddate><creator>Chennoufi, Ilham</creator><creator>Bendiouri, Reda</creator><creator>Lachkar, Azeddine</creator><creator>Drissia, Belfadil</creator><creator>Abdenbi Tsen, Adil</creator><creator>Elayoubi, Fahd</creator><creator>Ghailan, Rachid</creator><general>Elsevier Ltd</general><general>Elsevier</general><scope>6I.</scope><scope>AAFTH</scope><scope>NPM</scope><scope>AAYXX</scope><scope>CITATION</scope><scope>5PM</scope><orcidid>https://orcid.org/0000-0002-2862-8102</orcidid><orcidid>https://orcid.org/0000-0002-2325-4930</orcidid></search><sort><creationdate>20210901</creationdate><title>Adult-onset woakes' syndrome: Report of two cases</title><author>Chennoufi, Ilham ; Bendiouri, Reda ; Lachkar, Azeddine ; Drissia, Belfadil ; Abdenbi Tsen, Adil ; Elayoubi, Fahd ; Ghailan, Rachid</author></sort><facets><frbrtype>5</frbrtype><frbrgroupid>cdi_FETCH-LOGICAL-c373t-311dbb551ba66c2c2bf0bbf0fbd7dc7ba2fc51715ef7abd9d329d5043182a0883</frbrgroupid><rsrctype>articles</rsrctype><prefilter>articles</prefilter><language>eng</language><creationdate>2021</creationdate><topic>Adult male</topic><topic>Case Report</topic><topic>Digital compression</topic><topic>Nasal dorsum deformity</topic><topic>Nasal polyps</topic><topic>Sinonasal surgery</topic><topic>Woakes' syndrome</topic><toplevel>peer_reviewed</toplevel><toplevel>online_resources</toplevel><creatorcontrib>Chennoufi, Ilham</creatorcontrib><creatorcontrib>Bendiouri, Reda</creatorcontrib><creatorcontrib>Lachkar, Azeddine</creatorcontrib><creatorcontrib>Drissia, Belfadil</creatorcontrib><creatorcontrib>Abdenbi Tsen, Adil</creatorcontrib><creatorcontrib>Elayoubi, Fahd</creatorcontrib><creatorcontrib>Ghailan, Rachid</creatorcontrib><collection>ScienceDirect Open Access Titles</collection><collection>Elsevier:ScienceDirect:Open Access</collection><collection>PubMed</collection><collection>CrossRef</collection><collection>PubMed Central (Full Participant titles)</collection><jtitle>Annals of medicine and surgery</jtitle></facets><delivery><delcategory>Remote Search Resource</delcategory><fulltext>fulltext</fulltext></delivery><addata><au>Chennoufi, Ilham</au><au>Bendiouri, Reda</au><au>Lachkar, Azeddine</au><au>Drissia, Belfadil</au><au>Abdenbi Tsen, Adil</au><au>Elayoubi, Fahd</au><au>Ghailan, Rachid</au><format>journal</format><genre>article</genre><ristype>JOUR</ristype><atitle>Adult-onset woakes' syndrome: Report of two cases</atitle><jtitle>Annals of medicine and surgery</jtitle><addtitle>Ann Med Surg (Lond)</addtitle><date>2021-09-01</date><risdate>2021</risdate><volume>69</volume><spage>102695</spage><pages>102695-</pages><artnum>102695</artnum><issn>2049-0801</issn><eissn>2049-0801</eissn><abstract>Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases.
We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed.
having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed.
These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery.
•Woakes' syndrome is an extremely rare clinical condition.•Self-medication and chronic evolution seemed to be factors to develop woakes' syndrome.•External nose deformity may be successfully corrected by forced external digital compression without osteotomies.</abstract><cop>England</cop><pub>Elsevier Ltd</pub><pmid>34457252</pmid><doi>10.1016/j.amsu.2021.102695</doi><orcidid>https://orcid.org/0000-0002-2862-8102</orcidid><orcidid>https://orcid.org/0000-0002-2325-4930</orcidid><oa>free_for_read</oa></addata></record> |
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subjects | Adult male Case Report Digital compression Nasal dorsum deformity Nasal polyps Sinonasal surgery Woakes' syndrome |
title | Adult-onset woakes' syndrome: Report of two cases |
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