Adult-onset woakes' syndrome: Report of two cases

Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two ne...

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Veröffentlicht in:Annals of medicine and surgery 2021-09, Vol.69, p.102695, Article 102695
Hauptverfasser: Chennoufi, Ilham, Bendiouri, Reda, Lachkar, Azeddine, Drissia, Belfadil, Abdenbi Tsen, Adil, Elayoubi, Fahd, Ghailan, Rachid
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container_title Annals of medicine and surgery
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creator Chennoufi, Ilham
Bendiouri, Reda
Lachkar, Azeddine
Drissia, Belfadil
Abdenbi Tsen, Adil
Elayoubi, Fahd
Ghailan, Rachid
description Woakes' syndrome is a rare condition commonly defined as recurrent sinonasal polyposis with consecutive destruction of the nasal pyramid. Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases. We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed. having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. Surgical treatment of the nasal dorsum deformity is rarely addressed. These observations suggest that the external nose deformity may be successfully corrected by digital compression, in combination with endoscopic sinus surgery. •Woakes' syndrome is an extremely rare clinical condition.•Self-medication and chronic evolution seemed to be factors to develop woakes' syndrome.•External nose deformity may be successfully corrected by forced external digital compression without osteotomies.
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Till now, only a few cases have been reported in the literature. The purpose of this paper is to present the features of woakes' syndrome through two new clinical cases, adding some valuable insight to the recently reported cases. We report a series of two consecutive adults male and female patients, aged 55 and 58 years, with Samter's triad, who presented recurrent nasal polyposis and progressive broadening of the nasal dorsum. Facial CT showed in both patients the same radiologic pattern of nasal and paranasal cavities obliteration with nasal bone deformation. Both patients underwent functional endoscopic sinus surgery and correction of the bony nasal vault deformity without osteotomies. At 3 months follow-up, the nasal air passage remained free and aesthetic outcomes were observed. having been described over 130 years ago, the etiology of woakes' syndrome remains unclear. Treatment includes topical treatment and sinonasal surgery. 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subjects Adult male
Case Report
Digital compression
Nasal dorsum deformity
Nasal polyps
Sinonasal surgery
Woakes' syndrome
title Adult-onset woakes' syndrome: Report of two cases
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