Transplantation of iPSC-derived TM cells rescues glaucoma phenotypes in vivo

Glaucoma is a common cause of vision loss or blindness and reduction of intraocular pressure (IOP) has been proven beneficial in a large fraction of glaucoma patients. The IOP is maintained by the trabecular meshwork (TM) and the elevation of IOP in open-angle glaucoma is associated with dysfunction...

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Veröffentlicht in:Proceedings of the National Academy of Sciences - PNAS 2016-06, Vol.113 (25), p.E3492-E3500
Hauptverfasser: Zhu, Wei, Gramlich, Oliver W., Laboissonniere, Lauren, Jain, Ankur, Sheffield, Val C., Trimarchi, Jeffrey M., Tucker, Budd A., Kuehn, Markus H.
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container_issue 25
container_start_page E3492
container_title Proceedings of the National Academy of Sciences - PNAS
container_volume 113
creator Zhu, Wei
Gramlich, Oliver W.
Laboissonniere, Lauren
Jain, Ankur
Sheffield, Val C.
Trimarchi, Jeffrey M.
Tucker, Budd A.
Kuehn, Markus H.
description Glaucoma is a common cause of vision loss or blindness and reduction of intraocular pressure (IOP) has been proven beneficial in a large fraction of glaucoma patients. The IOP is maintained by the trabecular meshwork (TM) and the elevation of IOP in open-angle glaucoma is associated with dysfunction and loss of the postmitotic cells residing within this tissue. To determine if IOP control can be maintained by replacing lost TM cells, we transplanted TM-like cells derived from induced pluripotent stem cells into the anterior chamber of a transgenic mouse model of glaucoma. Transplantation led to significantly reduced IOP and improved aqueous humor outflow facility, which was sustained for at least 9 wk. The ability to maintain normal IOP engendered survival of retinal ganglion cells, whose loss is ultimately the cause for reduced vision in glaucoma. In vivo and in vitro analyses demonstrated higher TM cellularity in treated mice compared with littermate controls and indicated that this increase is primarily because of a proliferative response of endogenous TM cells. Thus, our study provides in vivo demonstration that regeneration of the glaucomatous TM is possible and points toward novel approaches in the treatment of this disease.
doi_str_mv 10.1073/pnas.1604153113
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The IOP is maintained by the trabecular meshwork (TM) and the elevation of IOP in open-angle glaucoma is associated with dysfunction and loss of the postmitotic cells residing within this tissue. To determine if IOP control can be maintained by replacing lost TM cells, we transplanted TM-like cells derived from induced pluripotent stem cells into the anterior chamber of a transgenic mouse model of glaucoma. Transplantation led to significantly reduced IOP and improved aqueous humor outflow facility, which was sustained for at least 9 wk. The ability to maintain normal IOP engendered survival of retinal ganglion cells, whose loss is ultimately the cause for reduced vision in glaucoma. In vivo and in vitro analyses demonstrated higher TM cellularity in treated mice compared with littermate controls and indicated that this increase is primarily because of a proliferative response of endogenous TM cells. 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source Jstor Complete Legacy; MEDLINE; PubMed Central; Alma/SFX Local Collection; Free Full-Text Journals in Chemistry
subjects Animals
Biological Sciences
Blindness
Cytoskeletal Proteins - genetics
Disease Models, Animal
Eye Proteins - genetics
Genotype & phenotype
Glaucoma
Glaucoma - pathology
Glaucoma - physiopathology
Glaucoma - therapy
Glycoproteins - genetics
Humans
Intraocular Pressure
Mice
Mice, Transgenic
Mutation
PNAS Plus
Rodents
Stem Cell Transplantation
Stem cells
Trabecular Meshwork - pathology
title Transplantation of iPSC-derived TM cells rescues glaucoma phenotypes in vivo
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