Apparent regression of the CGG repeat in FMR1 to an allele of normal size

The fragile X syndrome is the result of amplification of a CGG trinucleotide repeat in the FMR1 gene and anticipation in this disease is caused by an intergenerational expansion of this repeat. Although regression of a CGG repeat in the premutation range is not uncommon, regression from a full premu...

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Veröffentlicht in:Human genetics 1994-11, Vol.94 (5), p.523-526
Hauptverfasser: Vits, L, De Boulle, K, Reyniers, E, Handig, I, Darby, J K, Oostra, B, Willems, P J
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container_end_page 526
container_issue 5
container_start_page 523
container_title Human genetics
container_volume 94
creator Vits, L
De Boulle, K
Reyniers, E
Handig, I
Darby, J K
Oostra, B
Willems, P J
description The fragile X syndrome is the result of amplification of a CGG trinucleotide repeat in the FMR1 gene and anticipation in this disease is caused by an intergenerational expansion of this repeat. Although regression of a CGG repeat in the premutation range is not uncommon, regression from a full premutation (> 200 repeats) or premutation range (50-200 repeats) to a repeat of normal size (< 50 repeats) has not yet been documented. We present here a family in which the number of repeats apparently regressed from approximately 110 in the mother to 44 in her daughter. Although the CGG repeat of the daughter is in the normal range, she is a carrier of the fragile X mutation based upon the segregation pattern of Xq27 markers flanking FMR1. It is unclear, however, whether this allele of 44 repeats will be stably transmitted, as the daughter has as yet no progeny. Nevertheless, the size range between normal alleles and premutation alleles overlap, a factor that complicates genetic counseling.
doi_str_mv 10.1007/BF00211019
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subjects Alleles
Female
Fragile X Mental Retardation Protein
Fragile X Syndrome - genetics
Haplotypes
Heterozygote
Humans
Male
Mutation - genetics
Nerve Tissue Proteins - genetics
Pedigree
Repetitive Sequences, Nucleic Acid - genetics
RNA-Binding Proteins
title Apparent regression of the CGG repeat in FMR1 to an allele of normal size
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