Congenital cystic adenomatoid malformation of lung type 1

Abstract Congenital cystic adenomatoid malformation, a rare developmental, hamartomatous abnormality of the lung, usually is unilateral, is localized, and presents in early infancy. Delayed occurrence in older children and multilobar involvement are rare. We describe a case of congenital cystic aden...

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Veröffentlicht in:Journal of pediatric surgery 2010-02, Vol.45 (2), p.e25-e28
Hauptverfasser: Mathai, Alka Mary, Kini, Hema, Pai, Muktha R, Shetty, Ashok B, Murali, Nirupama
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container_end_page e28
container_issue 2
container_start_page e25
container_title Journal of pediatric surgery
container_volume 45
creator Mathai, Alka Mary
Kini, Hema
Pai, Muktha R
Shetty, Ashok B
Murali, Nirupama
description Abstract Congenital cystic adenomatoid malformation, a rare developmental, hamartomatous abnormality of the lung, usually is unilateral, is localized, and presents in early infancy. Delayed occurrence in older children and multilobar involvement are rare. We describe a case of congenital cystic adenomatoid malformation type 1 with multilobar involvement, associated emphysema, and coexistent tracheobronchopathia osteochondroplastica in an adolescent girl for whom the correct diagnosis was achieved only on histologic examination. The importance of an accurate diagnosis of this entity enables proper subtyping, management to minimize the risk of infections and malignancy, and exclusion of associated malformations.
doi_str_mv 10.1016/j.jpedsurg.2009.11.022
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Delayed occurrence in older children and multilobar involvement are rare. We describe a case of congenital cystic adenomatoid malformation type 1 with multilobar involvement, associated emphysema, and coexistent tracheobronchopathia osteochondroplastica in an adolescent girl for whom the correct diagnosis was achieved only on histologic examination. 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subjects Abnormalities, Multiple - diagnosis
Abnormalities, Multiple - epidemiology
Abnormalities, Multiple - pathology
Adolescent
CCAM type 1
Comorbidity
Cystic Adenomatoid Malformation of Lung, Congenital - diagnosis
Cystic Adenomatoid Malformation of Lung, Congenital - epidemiology
Cystic Adenomatoid Malformation of Lung, Congenital - pathology
Diagnosis, Differential
Emphysema
Female
Functional Laterality
Humans
Lung
Lung - pathology
Lung - surgery
Multilobar
Pediatrics
Pneumonectomy
Pulmonary Emphysema - epidemiology
Pulmonary Emphysema - pathology
Surgery
Tracheobronchomalacia - diagnosis
Tracheobronchomalacia - epidemiology
Tracheobronchomalacia - pathology
Tracheobronchopathia osteochondroplastica
title Congenital cystic adenomatoid malformation of lung type 1
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