Clinical findings of a myoclonus-dystonia family with two distinct mutations

Myoclonus-dystonia has recently been associated with mutations in the epsilon-sarcoglycan gene (SCGE) on 7q21. Previously, the authors reported a patient with myoclonus-dystonia and an 18-bp deletion in the DYT1 gene on 9q34. The authors have now re-evaluated the patient harboring this deletion for...

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Veröffentlicht in:Neurology 2002-10, Vol.59 (8), p.1244-1246
Hauptverfasser: DOHENY, D, DANISI, F, BREAKEFIELD, X. O, BRIN, M. F, SILVERMAN, J. M, SMITH, C, MORRISON, C, VELICKOVIC, M, DE LEON, D, BRESSMAN, S. B, LEUNG, J, OZELIUS, L, KLEIN, C
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container_end_page 1246
container_issue 8
container_start_page 1244
container_title Neurology
container_volume 59
creator DOHENY, D
DANISI, F
BREAKEFIELD, X. O
BRIN, M. F
SILVERMAN, J. M
SMITH, C
MORRISON, C
VELICKOVIC, M
DE LEON, D
BRESSMAN, S. B
LEUNG, J
OZELIUS, L
KLEIN, C
description Myoclonus-dystonia has recently been associated with mutations in the epsilon-sarcoglycan gene (SCGE) on 7q21. Previously, the authors reported a patient with myoclonus-dystonia and an 18-bp deletion in the DYT1 gene on 9q34. The authors have now re-evaluated the patient harboring this deletion for mutations in the SGCE gene and identified a missense change. In the current study, the authors describe the clinical details of this family carrying mutations in two different dystonia genes. Further analysis of these mutations separately and together in cell culture and in animal models should clarify their functional consequences.
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subjects Adolescent
Biological and medical sciences
Carrier Proteins - genetics
Cytoskeletal Proteins - genetics
Dystonia - genetics
Dystonia - psychology
Female
Humans
Male
Medical sciences
Membrane Glycoproteins - genetics
Middle Aged
Molecular Chaperones
Mutation - genetics
Myoclonus - genetics
Myoclonus - psychology
Nervous system (semeiology, syndromes)
Nervous system as a whole
Neurology
Neuropsychological Tests
Pedigree
Sarcoglycans
title Clinical findings of a myoclonus-dystonia family with two distinct mutations
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