The future of cystic fibrosis treatment: from disease mechanisms to novel therapeutic approaches

With the 2019 breakthrough in the development of highly effective modulator therapy providing unprecedented clinical benefits for over 90% of patients with cystic fibrosis who are genetically eligible for treatment, this rare disease has become a front runner of transformative molecular therapy. Thi...

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Veröffentlicht in:The Lancet (British edition) 2023-09, Vol.402 (10408), p.1185-1198
Hauptverfasser: Graeber, Simon Y, Mall, Marcus A
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creator Graeber, Simon Y
Mall, Marcus A
description With the 2019 breakthrough in the development of highly effective modulator therapy providing unprecedented clinical benefits for over 90% of patients with cystic fibrosis who are genetically eligible for treatment, this rare disease has become a front runner of transformative molecular therapy. This success is based on fundamental research, which led to the identification of the disease-causing CFTR gene and our subsequent understanding of the disease mechanisms underlying the pathogenesis of cystic fibrosis, working together with a continuously evolving clinical research and drug development pipeline. In this Series paper, we focus on advances since 2018, and remaining knowledge gaps in our understanding of the molecular mechanisms of CFTR dysfunction in the airway epithelium and their links to mucus dysfunction, impaired host defences, airway infection, and chronic inflammation of the lungs of people with cystic fibrosis. We review progress in (and the remaining obstacles to) pharmacological approaches to rescue CFTR function, and novel strategies for improved symptomatic therapies for cystic fibrosis, including how these might be applicable to common lung diseases, such as bronchiectasis and chronic obstructive pulmonary disease. Finally, we discuss the promise of genetic therapies and gene editing approaches to restore CFTR function in the lungs of all patients with cystic fibrosis independent of their CFTR genotype, and the unprecedented opportunities to transform cystic fibrosis from a fatal disease to a treatable and potentially curable one.
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subjects Bronchiectasis
Chloride
Chronic infection
Chronic obstructive pulmonary disease
Cystic fibrosis
Cystic fibrosis transmembrane conductance regulator
Drug development
Epithelium
Genetic modification
Genome editing
Genotypes
Health services
Homeostasis
Kinases
Lung diseases
Lungs
Molecular modelling
Mutation
Obstructive lung disease
Pathogenesis
Patients
Precision medicine
Proteins
Recovery of function
Respiratory tract
title The future of cystic fibrosis treatment: from disease mechanisms to novel therapeutic approaches
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