Development challenges associated with rAAV-based gene therapies

The number of gene therapies in development continues to increase, as they represent a novel method to treat, and potentially cure, many diseases. Gene therapies can be conducted with an in vivo or ex vivo approach, to cause gene augmentation, gene suppression, or genomic editing. Adeno-associated v...

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Veröffentlicht in:Journal of toxicological sciences 2021, Vol.46(2), pp.57-68
Hauptverfasser: Bolt, Michael W., Brady, Joseph T., Whiteley, Lawrence O., Khan, K. Nasir
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creator Bolt, Michael W.
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Khan, K. Nasir
description The number of gene therapies in development continues to increase, as they represent a novel method to treat, and potentially cure, many diseases. Gene therapies can be conducted with an in vivo or ex vivo approach, to cause gene augmentation, gene suppression, or genomic editing. Adeno-associated viruses are commonly used to deliver gene therapies, but their use is associated with several manufacturing, nonclinical and clinical challenges. As these challenges emerge, regulatory agency expectations continue to evolve. Following administration of rAAV-based gene therapies, nonclinical toxicities may occur, which includes immunogenicity, hepatotoxicity, neurotoxicity, and the potential risks for insertional mutagenesis and subsequent tumorgenicity. The mechanism for these findings and translation into the clinical setting are unclear at this time but have influenced the nonclinical studies that regulatory agencies are increasingly requesting to support clinical trials and marketing authorizations. These evolving regulatory expectations and toxicities, as well as future nonclinical considerations, are discussed herein.
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source Elektronische Zeitschriftenbibliothek - Frei zugängliche E-Journals; J-STAGE (Japan Science & Technology Information Aggregator, Electronic) Freely Available Titles - Japanese; Free Full-Text Journals in Chemistry
subjects AAV gene therapy
Clinical trials
Development challenges
Gene therapy
Genomics
Hepatotoxicity
Immunogenicity
Insertional mutagenesis
Neurotoxicity
Nonclinical toxicity
Viruses
title Development challenges associated with rAAV-based gene therapies
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