A Case Report of Caudal Regression Syndrome Associated with an Intraspinal Arachnoid Cyst
We report here a rare case of caudal regression syndrome associated with an intraspinal arachnoid cyst. The patient was a 6-month-old baby girl with multicomplex congenital abnormalities: sacrococcygeal dysgenesis and ventral curvature, large terminal cyst (myelocystocele), spinal arachnoid cyst, ce...
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| Veröffentlicht in: | Pediatric neurosurgery 1999-10, Vol.31 (4), p.207-212 |
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| container_title | Pediatric neurosurgery |
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| creator | Tsugu, Hitoshi Fukushima, Takeo Oshiro, Shinya Tomonaga, Masamichi Utsunomiya, Hidetsuna Oshima, Kazuhiro Ohjimi, Hiroyuki |
| description | We report here a rare case of caudal regression syndrome associated with an intraspinal arachnoid cyst. The patient was a 6-month-old baby girl with multicomplex congenital abnormalities: sacrococcygeal dysgenesis and ventral curvature, large terminal cyst (myelocystocele), spinal arachnoid cyst, cerebellar hypertrophy (suspected), high imperforate anus, partial dysgenesis of the large intestine, omphalocele, atresia of the vagina, bilateral incomplete ureter duplication, incomplete pseudoduplicated bladder and bilateral talipes equinovarus. We performed plastic repair of the myelocystocele and perineal lesion for caudal regression syndrome and partial removal of the cyst wall for the intraspinal arachnoid cyst. She has been well for 3 years postoperatively, and her mental development is normal. |
| doi_str_mv | 10.1159/000028863 |
| format | Article |
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The patient was a 6-month-old baby girl with multicomplex congenital abnormalities: sacrococcygeal dysgenesis and ventral curvature, large terminal cyst (myelocystocele), spinal arachnoid cyst, cerebellar hypertrophy (suspected), high imperforate anus, partial dysgenesis of the large intestine, omphalocele, atresia of the vagina, bilateral incomplete ureter duplication, incomplete pseudoduplicated bladder and bilateral talipes equinovarus. We performed plastic repair of the myelocystocele and perineal lesion for caudal regression syndrome and partial removal of the cyst wall for the intraspinal arachnoid cyst. She has been well for 3 years postoperatively, and her mental development is normal.</description><identifier>ISSN: 1016-2291</identifier><identifier>EISSN: 1423-0305</identifier><identifier>DOI: 10.1159/000028863</identifier><identifier>PMID: 10705931</identifier><identifier>CODEN: PDNEEV</identifier><language>eng</language><publisher>Basel, Switzerland: Karger</publisher><subject>Abnormalities, Multiple - diagnosis ; Abnormalities, Multiple - pathology ; Abnormalities, Multiple - surgery ; Arachnoid Cysts - diagnosis ; Arachnoid Cysts - pathology ; Arachnoid Cysts - surgery ; Biological and medical sciences ; Case Report ; Female ; Follow-Up Studies ; Humans ; Infant ; Magnetic Resonance Imaging ; Malformations of the nervous system ; Medical sciences ; Neural Tube Defects - diagnosis ; Neural Tube Defects - pathology ; Neural Tube Defects - surgery ; Neurology ; Reoperation ; Sacrum - abnormalities ; Sacrum - pathology ; Spinal Cord - pathology ; Spinal Cord Compression - diagnosis ; Spinal Cord Compression - pathology ; Spinal Cord Compression - surgery ; Urogenital Abnormalities - diagnosis ; Urogenital Abnormalities - pathology ; Urogenital Abnormalities - surgery</subject><ispartof>Pediatric neurosurgery, 1999-10, Vol.31 (4), p.207-212</ispartof><rights>2000 S. Karger AG, Basel</rights><rights>2000 INIST-CNRS</rights><rights>Copyright (c) 1999 S. Karger AG, Basel</rights><lds50>peer_reviewed</lds50><woscitedreferencessubscribed>false</woscitedreferencessubscribed><citedby>FETCH-LOGICAL-c415t-4d4ac6db242edee669d9f70d7ccd0169197bdacb6d0c532ba0f8f359fede68cd3</citedby><cites>FETCH-LOGICAL-c415t-4d4ac6db242edee669d9f70d7ccd0169197bdacb6d0c532ba0f8f359fede68cd3</cites></display><links><openurl>$$Topenurl_article</openurl><openurlfulltext>$$Topenurlfull_article</openurlfulltext><thumbnail>$$Tsyndetics_thumb_exl</thumbnail><link.rule.ids>314,776,780,2423,27901,27902</link.rule.ids><backlink>$$Uhttp://pascal-francis.inist.fr/vibad/index.php?action=getRecordDetail&idt=1234429$$DView record in Pascal Francis$$Hfree_for_read</backlink><backlink>$$Uhttps://www.ncbi.nlm.nih.gov/pubmed/10705931$$D View this record in MEDLINE/PubMed$$Hfree_for_read</backlink></links><search><creatorcontrib>Tsugu, Hitoshi</creatorcontrib><creatorcontrib>Fukushima, Takeo</creatorcontrib><creatorcontrib>Oshiro, Shinya</creatorcontrib><creatorcontrib>Tomonaga, Masamichi</creatorcontrib><creatorcontrib>Utsunomiya, Hidetsuna</creatorcontrib><creatorcontrib>Oshima, Kazuhiro</creatorcontrib><creatorcontrib>Ohjimi, Hiroyuki</creatorcontrib><title>A Case Report of Caudal Regression Syndrome Associated with an Intraspinal Arachnoid Cyst</title><title>Pediatric neurosurgery</title><addtitle>Pediatr Neurosurg</addtitle><description>We report here a rare case of caudal regression syndrome associated with an intraspinal arachnoid cyst. The patient was a 6-month-old baby girl with multicomplex congenital abnormalities: sacrococcygeal dysgenesis and ventral curvature, large terminal cyst (myelocystocele), spinal arachnoid cyst, cerebellar hypertrophy (suspected), high imperforate anus, partial dysgenesis of the large intestine, omphalocele, atresia of the vagina, bilateral incomplete ureter duplication, incomplete pseudoduplicated bladder and bilateral talipes equinovarus. We performed plastic repair of the myelocystocele and perineal lesion for caudal regression syndrome and partial removal of the cyst wall for the intraspinal arachnoid cyst. She has been well for 3 years postoperatively, and her mental development is normal.</description><subject>Abnormalities, Multiple - diagnosis</subject><subject>Abnormalities, Multiple - pathology</subject><subject>Abnormalities, Multiple - surgery</subject><subject>Arachnoid Cysts - diagnosis</subject><subject>Arachnoid Cysts - pathology</subject><subject>Arachnoid Cysts - surgery</subject><subject>Biological and medical sciences</subject><subject>Case Report</subject><subject>Female</subject><subject>Follow-Up Studies</subject><subject>Humans</subject><subject>Infant</subject><subject>Magnetic Resonance Imaging</subject><subject>Malformations of the nervous system</subject><subject>Medical sciences</subject><subject>Neural Tube Defects - diagnosis</subject><subject>Neural Tube Defects - pathology</subject><subject>Neural Tube Defects - surgery</subject><subject>Neurology</subject><subject>Reoperation</subject><subject>Sacrum - abnormalities</subject><subject>Sacrum - pathology</subject><subject>Spinal Cord - pathology</subject><subject>Spinal Cord Compression - diagnosis</subject><subject>Spinal Cord Compression - pathology</subject><subject>Spinal Cord Compression - surgery</subject><subject>Urogenital Abnormalities - diagnosis</subject><subject>Urogenital Abnormalities - pathology</subject><subject>Urogenital Abnormalities - surgery</subject><issn>1016-2291</issn><issn>1423-0305</issn><fulltext>true</fulltext><rsrctype>article</rsrctype><creationdate>1999</creationdate><recordtype>article</recordtype><sourceid>EIF</sourceid><sourceid>8G5</sourceid><sourceid>BENPR</sourceid><sourceid>GUQSH</sourceid><sourceid>M2O</sourceid><recordid>eNqF0c1LHDEYB-AgLX4fehZKECn0MDZfk5kcl0WrICptPfQ0ZPKhY2cnY94ZZP97s-6yKyJ0LpkkT978wovQF0pOKc3VD5I-VpaSb6FdKhjPCCf5p_RPqMwYU3QH7QE8EpKwEttoh5KC5IrTXfR3gqcaHP7l-hAHHHyajla3aeE-OoAmdPj3vLMxzByeAATT6MFZ_NwMD1h3-LIbooa-6dKRSdTmoQuNxdM5DAfos9ctuMPVuI_uzs_-TC-yq5ufl9PJVWYEzYdMWKGNtDUTzFnnpFRW-YLYwhib4iuqitpqU0tLTM5ZrYkvPc-VT1qWxvJ99G1Zt4_haXQwVLMGjGtb3bkwQiWVEGWq8l_IiGKqEAt4_A4-hjGmFybDUmgm-QJ9XyITA0B0vupjM9NxXlFSLbpSrbuS7NdVwbGeOftGLtuQwMkKaDC69VF3poGNY1wIpjbB_ul47-J6__b67PWiqrc-oaMP0TLKCyhcp-s</recordid><startdate>19991001</startdate><enddate>19991001</enddate><creator>Tsugu, Hitoshi</creator><creator>Fukushima, Takeo</creator><creator>Oshiro, Shinya</creator><creator>Tomonaga, Masamichi</creator><creator>Utsunomiya, Hidetsuna</creator><creator>Oshima, Kazuhiro</creator><creator>Ohjimi, Hiroyuki</creator><general>Karger</general><general>S. 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Tomonaga, Masamichi ; Utsunomiya, Hidetsuna ; Oshima, Kazuhiro ; Ohjimi, Hiroyuki</author></sort><facets><frbrtype>5</frbrtype><frbrgroupid>cdi_FETCH-LOGICAL-c415t-4d4ac6db242edee669d9f70d7ccd0169197bdacb6d0c532ba0f8f359fede68cd3</frbrgroupid><rsrctype>articles</rsrctype><prefilter>articles</prefilter><language>eng</language><creationdate>1999</creationdate><topic>Abnormalities, Multiple - diagnosis</topic><topic>Abnormalities, Multiple - pathology</topic><topic>Abnormalities, Multiple - surgery</topic><topic>Arachnoid Cysts - diagnosis</topic><topic>Arachnoid Cysts - pathology</topic><topic>Arachnoid Cysts - surgery</topic><topic>Biological and medical sciences</topic><topic>Case Report</topic><topic>Female</topic><topic>Follow-Up Studies</topic><topic>Humans</topic><topic>Infant</topic><topic>Magnetic Resonance Imaging</topic><topic>Malformations of the nervous system</topic><topic>Medical sciences</topic><topic>Neural Tube Defects - diagnosis</topic><topic>Neural Tube Defects - pathology</topic><topic>Neural Tube Defects - surgery</topic><topic>Neurology</topic><topic>Reoperation</topic><topic>Sacrum - abnormalities</topic><topic>Sacrum - pathology</topic><topic>Spinal Cord - pathology</topic><topic>Spinal Cord Compression - diagnosis</topic><topic>Spinal Cord Compression - pathology</topic><topic>Spinal Cord Compression - surgery</topic><topic>Urogenital Abnormalities - diagnosis</topic><topic>Urogenital Abnormalities - pathology</topic><topic>Urogenital Abnormalities - surgery</topic><toplevel>peer_reviewed</toplevel><toplevel>online_resources</toplevel><creatorcontrib>Tsugu, Hitoshi</creatorcontrib><creatorcontrib>Fukushima, Takeo</creatorcontrib><creatorcontrib>Oshiro, Shinya</creatorcontrib><creatorcontrib>Tomonaga, Masamichi</creatorcontrib><creatorcontrib>Utsunomiya, Hidetsuna</creatorcontrib><creatorcontrib>Oshima, Kazuhiro</creatorcontrib><creatorcontrib>Ohjimi, Hiroyuki</creatorcontrib><collection>Pascal-Francis</collection><collection>Medline</collection><collection>MEDLINE</collection><collection>MEDLINE (Ovid)</collection><collection>MEDLINE</collection><collection>MEDLINE</collection><collection>PubMed</collection><collection>CrossRef</collection><collection>ProQuest Central (Corporate)</collection><collection>Neurosciences Abstracts</collection><collection>Health & Medical Collection</collection><collection>ProQuest Central (purchase pre-March 2016)</collection><collection>Medical Database (Alumni Edition)</collection><collection>ProQuest Pharma Collection</collection><collection>Hospital Premium Collection</collection><collection>Hospital Premium Collection (Alumni Edition)</collection><collection>ProQuest Central (Alumni) (purchase pre-March 2016)</collection><collection>Research Library (Alumni Edition)</collection><collection>ProQuest Central (Alumni Edition)</collection><collection>ProQuest Central UK/Ireland</collection><collection>ProQuest Central Essentials</collection><collection>ProQuest Central</collection><collection>ProQuest One Community College</collection><collection>ProQuest Central Korea</collection><collection>Health Research Premium Collection</collection><collection>Health Research Premium Collection (Alumni)</collection><collection>ProQuest Central Student</collection><collection>Research Library Prep</collection><collection>ProQuest Health & Medical Complete (Alumni)</collection><collection>ABI/INFORM Professional Advanced</collection><collection>Health & Medical Collection (Alumni Edition)</collection><collection>Medical Database</collection><collection>Research Library</collection><collection>Research Library (Corporate)</collection><collection>ProQuest One Academic Eastern Edition (DO NOT USE)</collection><collection>ProQuest One Academic</collection><collection>ProQuest One Academic UKI Edition</collection><collection>ProQuest Central China</collection><collection>ProQuest Central Basic</collection><collection>MEDLINE - Academic</collection><jtitle>Pediatric neurosurgery</jtitle></facets><delivery><delcategory>Remote Search Resource</delcategory><fulltext>fulltext</fulltext></delivery><addata><au>Tsugu, Hitoshi</au><au>Fukushima, Takeo</au><au>Oshiro, Shinya</au><au>Tomonaga, Masamichi</au><au>Utsunomiya, Hidetsuna</au><au>Oshima, Kazuhiro</au><au>Ohjimi, Hiroyuki</au><format>journal</format><genre>article</genre><ristype>JOUR</ristype><atitle>A Case Report of Caudal Regression Syndrome Associated with an Intraspinal Arachnoid Cyst</atitle><jtitle>Pediatric neurosurgery</jtitle><addtitle>Pediatr Neurosurg</addtitle><date>1999-10-01</date><risdate>1999</risdate><volume>31</volume><issue>4</issue><spage>207</spage><epage>212</epage><pages>207-212</pages><issn>1016-2291</issn><eissn>1423-0305</eissn><coden>PDNEEV</coden><abstract>We report here a rare case of caudal regression syndrome associated with an intraspinal arachnoid cyst. The patient was a 6-month-old baby girl with multicomplex congenital abnormalities: sacrococcygeal dysgenesis and ventral curvature, large terminal cyst (myelocystocele), spinal arachnoid cyst, cerebellar hypertrophy (suspected), high imperforate anus, partial dysgenesis of the large intestine, omphalocele, atresia of the vagina, bilateral incomplete ureter duplication, incomplete pseudoduplicated bladder and bilateral talipes equinovarus. We performed plastic repair of the myelocystocele and perineal lesion for caudal regression syndrome and partial removal of the cyst wall for the intraspinal arachnoid cyst. She has been well for 3 years postoperatively, and her mental development is normal.</abstract><cop>Basel, Switzerland</cop><pub>Karger</pub><pmid>10705931</pmid><doi>10.1159/000028863</doi><tpages>6</tpages></addata></record> |
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| ispartof | Pediatric neurosurgery, 1999-10, Vol.31 (4), p.207-212 |
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| source | Karger Journals; MEDLINE |
| subjects | Abnormalities, Multiple - diagnosis Abnormalities, Multiple - pathology Abnormalities, Multiple - surgery Arachnoid Cysts - diagnosis Arachnoid Cysts - pathology Arachnoid Cysts - surgery Biological and medical sciences Case Report Female Follow-Up Studies Humans Infant Magnetic Resonance Imaging Malformations of the nervous system Medical sciences Neural Tube Defects - diagnosis Neural Tube Defects - pathology Neural Tube Defects - surgery Neurology Reoperation Sacrum - abnormalities Sacrum - pathology Spinal Cord - pathology Spinal Cord Compression - diagnosis Spinal Cord Compression - pathology Spinal Cord Compression - surgery Urogenital Abnormalities - diagnosis Urogenital Abnormalities - pathology Urogenital Abnormalities - surgery |
| title | A Case Report of Caudal Regression Syndrome Associated with an Intraspinal Arachnoid Cyst |
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