Eps8 regulates hair bundle length and functional maturation of mammalian auditory hair cells

Hair cells of the mammalian cochlea are specialized for the dynamic coding of sound stimuli. The transduction of sound waves into electrical signals depends upon mechanosensitive hair bundles that project from the cell's apical surface. Each stereocilium within a hair bundle is composed of unif...

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Veröffentlicht in:PLoS biology 2011-04, Vol.9 (4), p.e1001048
Hauptverfasser: Zampini, Valeria, Rüttiger, Lukas, Johnson, Stuart L, Franz, Christoph, Furness, David N, Waldhaus, Jörg, Xiong, Hao, Hackney, Carole M, Holley, Matthew C, Offenhauser, Nina, Di Fiore, Pier Paolo, Knipper, Marlies, Masetto, Sergio, Marcotti, Walter
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container_title PLoS biology
container_volume 9
creator Zampini, Valeria
Rüttiger, Lukas
Johnson, Stuart L
Franz, Christoph
Furness, David N
Waldhaus, Jörg
Xiong, Hao
Hackney, Carole M
Holley, Matthew C
Offenhauser, Nina
Di Fiore, Pier Paolo
Knipper, Marlies
Masetto, Sergio
Marcotti, Walter
description Hair cells of the mammalian cochlea are specialized for the dynamic coding of sound stimuli. The transduction of sound waves into electrical signals depends upon mechanosensitive hair bundles that project from the cell's apical surface. Each stereocilium within a hair bundle is composed of uniformly polarized and tightly packed actin filaments. Several stereociliary proteins have been shown to be associated with hair bundle development and function and are known to cause deafness in mice and humans when mutated. The growth of the stereociliar actin core is dynamically regulated at the actin filament barbed ends in the stereociliary tip. We show that Eps8, a protein with actin binding, bundling, and barbed-end capping activities in other systems, is a novel component of the hair bundle. Eps8 is localized predominantly at the tip of the stereocilia and is essential for their normal elongation and function. Moreover, we have found that Eps8 knockout mice are profoundly deaf and that IHCs, but not OHCs, fail to mature into fully functional sensory receptors. We propose that Eps8 directly regulates stereocilia growth in hair cells and also plays a crucial role in the physiological maturation of mammalian cochlear IHCs. Together, our results indicate that Eps8 is critical in coordinating the development and functionality of mammalian auditory hair cells.
doi_str_mv 10.1371/journal.pbio.1001048
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subjects Acoustic Stimulation
Actin
Action Potentials
Adaptor Proteins, Signal Transducing - genetics
Adaptor Proteins, Signal Transducing - metabolism
Animals
Biology
Calcium - metabolism
Calcium Channels - metabolism
Cell Surface Extensions - metabolism
Cell Surface Extensions - ultrastructure
Cochlea - cytology
Cochlea - growth & development
Cochlea - physiology
Cytoskeletal Proteins - genetics
Cytoskeletal Proteins - metabolism
Deafness
Deafness - genetics
Ears & hearing
Evoked Potentials, Auditory, Brain Stem
Exocytosis
Gene Deletion
Hair cells (Mechanoreceptors)
Hair Cells, Auditory - metabolism
Hair Cells, Auditory - ultrastructure
Mechanotransduction, Cellular
Mice
Mice, Inbred C57BL
Mice, Knockout
Physiological aspects
Potassium Channels - metabolism
Proteins
Rodents
title Eps8 regulates hair bundle length and functional maturation of mammalian auditory hair cells
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